Our aim was to study the incidence and outcome of antenatally detected renal malformations in rural Maharashtra. Among 7365 deliveries conducted during the study period, antenatal screening for renal malformations was done in 6682 (90.7 %) deliveries. Renal malformations were detected in 35 fetuses on antenatal screening. Postnatal investigations confirmed renal malformations in 27 babies (77.1%), giving an incidence of 0.4% among liveborn babies. Seven babies were operated and 2 were awaiting surgery (33.3%). Two patients expired and another two were lost to follow-up. The outcome was satisfactory in other patients. Antenatal screening was a useful tool in diagnosing renal malformations.